Successful treatment of Gorham-Stout syndrome in the spine by vertebroplasty with cement augmentation: A case report and literature review

Medicine
Shu-Zhong LiuYong Liu

Abstract

Gorham-Stout syndrome in the spine is extremely rare, and there is no standard curative management thus far. The objective of this article is to report a very rare case of Gorham-Stout syndrome of the lumbar and sacral spine with chylothorax and chyloperitoneum successfully treated by combination of vertebroplasty with cement augmentation and medication treatment. We described the clinical characteristics and postoperative therapy of the patient, and reviewed all of the published cases of Gorham-Stout syndrome of the lumbar and sacral spine. A 31-year-old man presented with increasingly serious abdominal distention and back pain. MRI showed massive bony destruction of the spine and pelvis. CT and ultrasonography demonstrated massive ascites and mild hydrothorax. We believe this is the first report of a case of Gorham-Stout syndrome with both chylothorax and chyloperitoneum. Chest and abdominal cavity puncture was performed for symptomatic relief and the test results confirmed chylothorax and chyloperitoneum. Tissue biopsy and percutaneous vertebroplasty at L5 were performed and the postoperative pathology together with symptoms and examinations were reported to be consistent with Gorham-Stout syndrome. Subsequently, we administ...Continue Reading

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Citations

Jan 14, 2020·Acta Orthopaedica·Kristian Nikolaus SchneiderDimosthenis Andreou
Jan 2, 2020·BMC Musculoskeletal Disorders·Chuanxi ZhengShiquan Zhang

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Methods Mentioned

BETA
percutaneous
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